Download PDF
Am J Perinatol 2002; 19(7): 395-400
DOI: 10.1055/s-2002-35610
Copyright © 2002 by Thieme Medical Publishers, Inc., 333 Seventh Avenue, New York, NY 10001, USA. Tel.: +1(212) 584-4662

Tracheal Agenesis: Report of Three Cases and Review of the Literature

Bibhuti B. Das1 , Anasuya Nagaraj1 , Andavolu H. Rao2 , Benamanahalli K. Rajegowda1
  • 1Department of Pediatrics, Lincoln Medical & Mental Health Center, Bronx, New York
  • 2Department of Pathology, The Medical Center at Princeton, Princeton, New Jersey
Further Information

Publication History

Publication Date:
20 November 2002 (online)

    Permissions and Reprints

ABSTRACT

Isolated type III tracheal agenesis without associated congenital anomalies is very rare. Therefore, infants with this type of isolated defects are potential candidates for surgical correction. We present three cases of tracheal agenesis (Floyd's type III) with no other major abnormalities and reviewed the literature. We also discussed the previously attempted surgical procedures with the hope that in future, with advances in surgical reconstruction, there may be a better solution for this lethal anomaly.

KEYWORDS

Tracheal agenesis - airway management

REFERENCES

  • 1 Floyd J, Campbell D C, Dominy D E. Agenesis of the trachea.  Am Rev Respir Dis . 1962;  86 557-560
    PubMedGoogle Scholar
  • 2 Manschot H J, van den Anker N J, Tibboel D. Tracheal agenesis.  Anaesthesia . 1994;  49 788-790
    PubMedGoogle Scholar
  • 3 Van Veenendaal B M, Liem K D, Marres H A. Congenital absence of the trachea.  Eur J Pediatr . 2000;  159 8-13
    CrossrefPubMedGoogle Scholar
  • 4 Kluth D, Steding G, Seidl W. The embryology of foregut malformations.  J Pediatr Surg . 1987;  22 389-393
    CrossrefPubMedGoogle Scholar
  • 5 Carlson B. Human Embryology and Developmental Biology.  2nd ed. St. Louis: Mosby 1999: 342-349
    Google Scholar
  • 6 Hiyama E, Yokoyama T, Ichikawa T, Matsuura Y. Surgical management of tracheal agenesis.  J Thorac Cardiovasc Surg . 1994;  108 830-833
    PubMedGoogle Scholar
  • 7 Sankaran K, Bhagirath C P, Bingham W T, Hjertaas R, Haight K. Tracheal atresia, proximal esophageal atresia, and distal tracheoesophageal fistula: report of two cases and review of literature.  Pediatrics . 1983;  71 821-823
    PubMedGoogle Scholar
  • 8 Soh H, Kawahawa H, Imura K. Tracheal agenesis in a child who survived for 6 years.  J Pediatr Surg . 1999;  34 1541-1543
    CrossrefPubMedGoogle Scholar
  • 9 Kutlu C A, Goldstraw P. Tracheobronchial sleeve resection with the use of a continuous anastomosis: results of one hundred consecutive cases.  J Thorac Cardiovasc Surg . 1999;  117 1112-1117
    PubMedGoogle Scholar
  • 10 Jacobs J P, Elliott M J, Haw M P, Bailey C M, Herberhold C. Pediatric tracheal homograft reconstruction: a novel approach to complex tracheal stenoses in children.  J Thorac Cardiovasc Surg . 1996;  112 1549-1558
    PubMedGoogle Scholar
  • 11 Fonkasrud E W, Martelle R R, Maloney J V. Surgical treatment of tracheal agenesis.  J Thorac Cardiovasc Surg . 1963;  45 520-525
    PubMedGoogle Scholar
  • 12 Altman R P, Randolph J G, Shearin R B. Tracheal agenesis: recognition and management.  J Pediatr Surg . 1972;  7 112-118
    CrossrefPubMedGoogle Scholar
  • 13 Hong S W, Baran G M, Schnafer L, Stool S E. Tracheal agenesis with bronchoesophageal fistula.  Laryngoscope . 1974;  83 250-254
    PubMedGoogle Scholar
  • 14 Buchino J J, Meagher P D, Cox J A. Tracheal agenesis: a clinical approach.  J Pediatr Surg . 1982;  17 132-137
    PubMedGoogle Scholar
  • 15 Rovira J, Morales L, Rottermann M. Agenesis of the trachea.  J Pediatr Surg . 1989;  24 1126-1127
    PubMedGoogle Scholar
  • 16 Lopez L, Serrano A, Varela A. Tracheal agenesis: an unresolved problem.  Thorac Cardiovasc Surg . 1991;  39 99-101
    PubMedGoogle Scholar
      >