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DOI: 10.1055/s-0035-1549581
Association of CFTR mutations with Cystic Fibrosis related Diabetes (CFRD) in Germany and Austria: a multicentre analysis from the DPV registry
Background: CF-related diabetes (CFRD) is a common comorbidity in cystic fibrosis (CF) and associated with negative outcome and increased mortality. In this study, we aimed to investigate current demographics of CFRD and the association of CFRD with C transmembrane conductance regulator (CFTR) genotypes.
Methods: Until September 2014, data of 777 patients with CFRD were included in the DPV-registry. Since 2013 the participating centres document the type of CFTR mutation additionally to diabetes-related parameters. Of 105 patients the CFTR mutation was available. Descriptive statistics were carried out using SAS 9.4. χ2-test and Wilcoxon-test was applied for group comparisons.
Results: At analysis, patients with CFRD had a median age of 19.3 [IQR: 16.5 – 26.1] years. The median age at CFRD primary diagnosis was 16.0 [13.4 – 20.6] years. Gender were 58% female and 42% male. Low bodyweight (BMI< 19 kg/m2) was present in 49.2% of cases. The most common CF mutation 'F508del homozygote' was present in 75.5% of CFRD patients (80/105). Compared to the latest national CF benchmarking report from 2012, this mutation was more common in CFRD patients (p < 0.001). The F508del/R553X was the second most frequent mutation with 4.7% (5/105) and the F508del/394delTT the third most frequent mutation with 2.8% (3/105) in CFRD patients.
Conclusion: In CF patients, CFRD is diagnosed mainly at young adolescent age. The most common CF mutation 'F508del homozygote' also represents the key risk factor for the development of CFRD.